Status:

TERMINATED

Single Ascending Dose Study of SAR439459 in Adults With Osteogenesis Imperfecta (OI)

Lead Sponsor:

Sanofi

Conditions:

Osteogenesis Imperfecta

Eligibility:

All Genders

18-65 years

Phase:

PHASE1

Brief Summary

SAR439459 is a human anti-Transforming growth factor β (TGFβ) monoclonal antibody. This phase 1 clinical study investigates the safety, tolerability, and activity of a single dose of SAR439459 in adul...

Detailed Description

The duration of the study for all participants will be approximately 29 weeks: * Up to 5 weeks from initiation of screening to dose administration * Treatment on Day 1 * Follow-up and observation of ...

Eligibility Criteria

Inclusion

  • Participants who are clinically categorized as Type I or IV osteogenesis imperfecta with a previously documented pathogenic genetic variant in human collagen type 1 alpha 1 gene (COL1A1) or human collagen type 1 alpha 2 gene (COL1A2).
  • Participants who have experienced at least 1 bone fracture in the past 10 years OR 2 or more (≥2) fractures since the age of 18.
  • Body weight ≥30.0 kg.
  • Contraception for sexually active male participants or female patient; not pregnant or breastfeeding; no sperm donating for male participant.
  • Signed written informed assent/consent.

Exclusion

  • Previously installed rods or metal hardware that would prevent bone mineral density evaluation of the lumbar spine (note: only two of the L1-L4 vertebrae are necessary for evaluation).
  • History of moderate (25-40°) to severe (\>40°) scoliosis assessed as Cobb angle (unless scoliosis does not impact assessment of bone mineral density in the lumbar vertebrae in the opinion of the investigator).
  • Postmenopausal women who:
  • Are within 5 years of the onset of menopause (for example less than 5 years from their last menstruation or post-hysterectomy), however if the person has been on hormone replacement therapy for more than 1 year prior to enrollment, then they are eligible regardless of time from onset of menopause. The person must be willing to continue hormone replacement therapy throughout the study duration. OR
  • Were previously on hormone replacement therapy but have stopped within the past 5 years.
  • History of treatment with denosumab, anti-sclerostin antibody, parathyroid hormone, bisphosphonates, or any other experimental therapy for OI within 6 months prior to any study baseline assessment.
  • Known bleeding disorder.
  • History of significant bleeding event that required hospitalization, surgery, or a blood transfusion that was possibly associated with increased bleeding tendency.
  • Any major surgery within the last 28 days prior to investigational medicinal product (IMP) administration.
  • Elective surgery or invasive procedure anticipated within 6 months after the IMP administration.
  • Therapeutic doses of anticoagulants or antiplatelet agents (eg, 1 mg/kg bid of enoxaparin, 300 mg of aspirin daily, and 75 mg of clopidogrel daily or equivalent) within 7 days prior to the IMP administration.
  • Any known central nervous system (CNS) or intraocular lesion that has a risk of bleeding.
  • Prior history of skin cancers including melanoma, squamous cell carcinoma, or basal cell carcinoma.
  • Clinically significant cardiac valvular disorder or symptomatic heart failure.
  • Vitamin D (25-hydoxyvitamin D) \<15 ng/dL; rescreening will be allowed after supplementation.
  • The above information is not intended to contain all considerations relevant to a potential participation in a clinical trial.

Key Trial Info

Start Date :

August 25 2022

Trial Type :

INTERVENTIONAL

Allocation :

ACTUAL

End Date :

November 12 2024

Estimated Enrollment :

16 Patients enrolled

Trial Details

Trial ID

NCT05231668

Start Date

August 25 2022

End Date

November 12 2024

Last Update

September 11 2025

Active Locations (13)

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Page 1 of 4 (13 locations)

1

UCLA Health_Site Number: 8400006

Los Angeles, California, United States, 90095

2

Yale University - Site Number:8400007

New Haven, Connecticut, United States, 06510

3

Indiana University School of Medicine_Site Number: 8400002

Indianapolis, Indiana, United States, 46202

4

Kennedy Krieger Institute_Site number 8400004

Baltimore, Maryland, United States, 21205