Status:

RECRUITING

Different Doses of Sirolimus for the Maintenance Treatment of Kaposiform Hemangioendothelioma

Lead Sponsor:

West China Hospital

Conditions:

Hemangioendothelioma

Eligibility:

All Genders

Up to 14 years

Phase:

PHASE2

Brief Summary

The purpose of this study is to compare the efficacy and safety of different doses of sirolimus in the maintenance treatment of kaposiform hemangioendothelioma.

Detailed Description

Kaposiform hemangioendothelioma (KHE) is a rare aggressive vascular neoplasm that occurs predominantly in infancy or early childhood, with an incidence of approximately 0.071/100,000. Currently, sirol...

Eligibility Criteria

Inclusion

  • Presenting a KHE with the following characteristics:
  • Male and female;
  • Between 0 and 14 years of age;
  • Diagnosis of KHE as determined by:
  • Biopsy;
  • Compatible MRI findings;
  • History and clinical features.
  • Patients were required to have adequate liver, renal and bone marrow function, and absence of active infection
  • Consent of parents (or the person with parental authority in families): signed and dated written informed consent.

Exclusion

  • Patients contraindicated for the administration of sirolimus (e.g., those with an allergy to sirolimus or other rapamycin analog)
  • Exposure to chemotherapy, embolization, corticosteroids, propranolol, sclerotherapy or any other investigational agents within 1 weeks before enrolment on study;
  • Patients had a history of a major surgery within 2 weeks before enrollment;
  • Patients who have a history of treatment with sirolimus or other mTOR inhibitor;
  • Any known evidence of significant local or systemic uncontrolled infection, defined as receiving intravenous antibiotics at the time of enrollment;
  • Concurrent severe and/or uncontrolled medical diseases that could compromise participation in the study (e.g. uncontrolled diabetes, uncontrolled hypertension, severe malnutrition, chronic liver or renal disease, active upper gastrointestinal tract ulceration).
  • Impairment of gastrointestinal function or chronic gastrointestinal disease that may significantly alter the absorption of sirolimus.
  • Patients with inadequate liver function:
  • Total bilirubin higher than or equal to 1.5 × the upper limit of the normal (ULN) for age and alanine aminotransferase and aspartate aminotransferase higher than or equal to 2.5 × the ULN for age.
  • Patients with inadequate renal function:
  • 0-5 years of age maximum serum creatinine (mg/dL) of 0.8; 6-10 years of age maximum serum creatinine (mg/dL) of 1.0; 11-14 years of age maximum serum creatinine (mg/dL) of 1.2;
  • Adequate bone marrow function:
  • Absolute neutrophil count lower than 1 × 109/L;
  • History of a malignancy within 5 years;
  • HIV infection or known immunodeficiency;
  • Indication for treatment with corticosteroids, vincristine, interferon-α, sirolimus, or tacrolimus for an indication other than IH;
  • Patients with an inability to participate in or follow-up during the study treatment and assessment plan;
  • Inability to give informed consent.

Key Trial Info

Start Date :

April 5 2022

Trial Type :

INTERVENTIONAL

Allocation :

ESTIMATED

End Date :

November 30 2025

Estimated Enrollment :

30 Patients enrolled

Trial Details

Trial ID

NCT05324384

Start Date

April 5 2022

End Date

November 30 2025

Last Update

January 24 2024

Active Locations (1)

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1

West China Hospital of Sichuan University

Chengdu, Sichuan, China, 610041