Status:

WITHDRAWN

A Natural History Study in Pediatric Participants With Hearing Loss Due to OTOF, GJB2, or GJB2/GJB6 Mutations

Lead Sponsor:

Regeneron Pharmaceuticals

Conditions:

Congenital Hearing Loss Secondary to Biallelic Mutations in the Otoferlin Gene (OTOF)

Biallelic Mutations in the Gap Junction Beta 2 (GJB2) Gene

Eligibility:

All Genders

Up to 7 years

Brief Summary

This is an observational study to examine the characteristics of gene-related hearing loss in pediatric participants with biallelic otoferlin (OTOF) Mutations, Gap Junction Beta 2 (GJB2) Mutations, or...

Detailed Description

Former Sponsor Decibel Therapeutics This is a longitudinal, retrospective and prospective, low interventional study designed to collect data on the natural history of pediatric participants with OTOF...

Eligibility Criteria

Inclusion

  • Participant is no older than 7 years (inclusive) at the time of the parent/legal guardian signing the informed consent form (ICF)
  • Participant has 1 of the following genotypes and meets the associated audiologic criteria based on physiologic and/or behavioral measures of inner ear function:
  • Biallelic pathogenic or likely pathogenic OTOF mutations with severe to profound sensorineural hearing loss (SNHL; ≥ 85 dB HL) and confirmed presence of OAEs
  • Biallelic pathogenic and truncating GJB2 mutation(s) with moderate or moderately-severe SNHL (≤41 to \<71 dB HL)
  • Digenic pathogenic or likely pathogenic mutations in GJB2 and GJB6 genes with mild or worse SNHL (\>26 dB HL)
  • Participant has at least 1 ear that has not received a cochlear implant (CI)

Exclusion

  • History of or active participation in an interventional trial related to hearing loss
  • History or presence of any other permanent/untreatable hearing loss conditions, including genetic conditions other than those involving biallelic OTOF or GJB2 mutations, or digenic GJB2/GJB6 mutations
  • History of treatment with ototoxic drugs

Key Trial Info

Start Date :

June 30 2025

Trial Type :

OBSERVATIONAL

Allocation :

ACTUAL

End Date :

June 30 2030

Estimated Enrollment :

Patients enrolled

Trial Details

Trial ID

NCT06019481

Start Date

June 30 2025

End Date

June 30 2030

Last Update

May 15 2025

Active Locations (2)

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Page 1 of 1 (2 locations)

1

Phoenix Childrens Hospital

Phoenix, Arizona, United States, 85016

2

Nationwide Children's Hospital

Columbus, Ohio, United States, 43205