Actively Recruiting

Age: 6Years - 21Years
All Genders
ID06500260

Natural History Study of Infants and Children With CNKSR2-Associated Neurodevelopmental Disorders and Epilepsy

Led by University of California, San Francisco · Updated on 2024-07-15

15

Participants Needed

1

Research Sites

N/A

Total Duration

On this page

AI-Summary

What this Trial Is About

Researchers are conducting a prospective natural history study focusing on children aged 6 to 21 years who have CNKSR2 mutations causing epilepsy aphasia syndrome (EAS) and intellectual disability (ID). The study aims to characterize the electroclinical, neurodevelopmental, and behavioral features of this condition. The collected data will serve as an external control for future clinical trials testing precision medicine treatments designed to improve seizures and neurodevelopmental outcomes in these patients. Participants will be observed without receiving investigational treatments, as this is an observational study. The research includes repeated assessments using advanced brain imaging techniques such as resting-state functional magnetic resonance imaging (fMRI), magnetoencephalography (MEG), and electroencephalography (EEG). These assessments occur at baseline, 12 months, and 24 months to track changes in brain connectivity, brain activity, and cortical responses related to speech and auditory feedback. During the study, children will undergo various evaluations including neurodevelopmental tests like the Bayley Scales of Infant and Toddler Development, Wechsler intelligence scales, Vineland Adaptive Behavior Scales, and attention and quality of life rating scales. These evaluations are scheduled across multiple time points over two years. Researchers will monitor changes in seizure-related brain activity, cognitive and behavioral functioning, and quality of life. The study is sponsored by the University of California, San Francisco, and aims to provide detailed natural history data to support future therapeutic trials.

CONDITIONS

Brief Title

CNKSR2 Natural History Study

Who Can Participate

Age: 6Years - 21Years
All Genders

Eligibility Criteria

Eligible

You may qualify if you...

  • Age between 6 and 21 years (inclusive) at time of consent
  • Confirmed CNKSR2 mutation demonstrated by genetic testing and confirmed by investigators
  • Confirmed intellectual disability or developmental delays as defined by the American Academy of Pediatrics
Not Eligible

You will not qualify if you...

  • Known pathogenic or clinically suspected mutation in a seizure-associated gene besides CNKSR2
  • Confirmed mutation in a gene besides CNKSR2 that increases severity of seizure phenotype
  • Known central nervous system structural abnormality confirmed by brain imaging not consistent with CNKSR2 EAS/ID clinical phenotype

AI-Screening

AI-Powered Screening

Complete this quick 3-step screening to check your eligibility

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Your Study Journey

Screening

Duration - 2 to 4 weeks

Participants are screened for eligibility to participate in the trial.

1 visit (in-person)

Diagnostic Evaluation

Duration - Baseline assessments

Participants undergo brain imaging and neurodevelopmental assessments to evaluate functional connectivity, brain activity, and developmental status.

1 baseline visit (in-person)

Long-term Monitoring

Duration - 24 months

Participants are monitored over 24 months with repeated assessments to track changes in brain function, neurodevelopment, and behavior.

Visits at Month 6, Month 12, Month 18, and Month 24

Trial Site Locations

Total: 1 location

1

University of California, San Francisco (UCSF)

San Francisco, California, United States, 94158

Actively Recruiting

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Research Team

A

Alex Fay, MD, PhD

M

Maya Dhar, MS

How is the study designed?

Study Type

OBSERVATIONAL

Masking

N/A

Allocation

N/A

Model

N/A

Primary Purpose

N/A

Number of Arms

0

Frequently Asked Questions

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