Actively Recruiting

Phase 1
Phase 2
Age: 18Years - 65Years
All Genders
ID05481879

A Randomized, Placebo-Controlled, Multiple Ascending Dose Study Assessing Safety, Tolerability, Pharmacodynamics, Efficacy, and Pharmacokinetics of DYNE-101 Administered to Participants With Myotonic Dystrophy Type 1

Led by Dyne Therapeutics · Updated on 2026-05-12

116

Participants Needed

20

Research Sites

N/A

Total Duration

On this page

AI-Summary

What this Trial Is About

Researchers are evaluating the safety and tolerability of multiple intravenous doses of DYNE-101 in adults with Myotonic Dystrophy Type 1 (DM1), a condition characterized by muscle symptoms and myotonia. This randomized, placebo-controlled study involves both multiple-ascending dose and dose expansion groups. The study is designed to better understand how DYNE-101 behaves in the body and its effects on muscle function and myotonia severity. The study includes four periods: a Screening Period lasting up to 8 weeks, a Placebo-Controlled Period of 24 weeks where participants receive either DYNE-101 or placebo by IV infusion every 4 or 8 weeks, a Treatment Period of 24 weeks where all participants receive DYNE-101, and a Long-Term Extension Period of up to 168 weeks where participants continue receiving DYNE-101. Dosing schedules vary between every 4 weeks (Q4W) and every 8 weeks (Q8W). Participants will undergo various assessments throughout the study, including tests of muscle function such as hand grip relaxation time, walk/run tests, and stair climbing, as well as muscle tissue analysis for myotonia and other biomarkers. Researchers will monitor safety by tracking adverse events and drug levels in the blood. The study lasts up to about 4 years, including long-term follow-up to evaluate the effects and safety of DYNE-101 over time.

CONDITIONS

Brief Title

Safety, Tolerability, Pharmacodynamic, Efficacy, and Pharmacokinetic Study of DYNE-101 in Participants With Myotonic Dystrophy Type 1

Who Can Participate

Age: 18Years - 65Years
All Genders

Eligibility Criteria

Eligible

You may qualify if you...

  • Diagnosis of Myotonic Dystrophy Type 1 (DM1) with trinucleotide repeat size greater than 100
  • Onset of DM1 muscle symptoms at age 12 years or older
  • Clinically noticeable muscle stiffness with hand opening time of at least 2 seconds
  • Hand grip and ankle dorsiflexion strength present
  • Able to complete 10-meter walk/run test, stair climbing (MAD cohorts only), and sit to stand test 5 times without assistive devices such as canes, walkers, or orthoses
Not Eligible

You will not qualify if you...

  • Major surgery within 12 weeks before starting the study or planned major surgery during the study
  • History of severe allergic reactions (anaphylaxis)
  • Medical conditions other than DM1 that affect walking or participation in functional tests
  • Use of medications that improve myotonia within 5 half-lives before screening
  • Abnormal electrocardiogram with certain heart conduction issues or prolonged QT interval
  • Forced vital capacity less than 50%
  • Tibialis anterior muscle biopsy within 3 months before Day 1 or planned biopsy during the study for unrelated reasons
  • History of suicide attempt, behavior, or significant suicidal thoughts within 6 months before screening
  • Use of GLP-1 agonist medications within 5 half-lives before screening
  • Significant weight loss during the study that could affect dosing or muscle function tests

AI-Screening

AI-Powered Screening

Complete this quick 3-step screening to check your eligibility

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Your Study Journey

Screening

Duration - 2 to 4 weeks

Participants are screened for eligibility to participate in the trial.

1 visit (in-person)

Treatment

Duration - Up to 24 weeks

Participants receive DYNE-101 or placebo by IV infusion once every 4 weeks or once every 8 weeks for up to 24 weeks in a randomized, placebo-controlled period. Participants who received placebo then receive DYNE-101 in a subsequent treatment period.

Infusions once every 4 or 8 weeks for up to 24 weeks

Treatment

Duration - Up to 24 weeks

Participants continue to receive DYNE-101 by IV infusion once every 4 weeks or once every 8 weeks for up to 24 weeks following the placebo-controlled period.

Infusions once every 4 or 8 weeks for up to 24 weeks

Long-term Monitoring

Duration - Up to 168 weeks

Participants receive DYNE-101 by IV infusion once every 4 weeks or once every 8 weeks for up to 168 weeks during a long-term extension period to assess safety and efficacy.

Infusions once every 4 or 8 weeks for up to 168 weeks

Trial Site Locations

Total: 20 locations

1

Stanford University

Stanford, California, United States, 94305

Actively Recruiting

2

University of Florida College of Medicine

Gainesville, Florida, United States, 32610

Actively Recruiting

3

Indiana University School of Medicine

Indianapolis, Indiana, United States, 46202

Actively Recruiting

4

University of Iowa

Iowa City, Iowa, United States, 52242

Actively Recruiting

5

Washington University in St. Louis

St Louis, Missouri, United States, 63110

Actively Recruiting

6

University of Rochester Medical Center

Rochester, New York, United States, 14642

Actively Recruiting

7

Neurology Rare Disease Center

Denton, Texas, United States, 76208

Actively Recruiting

8

Virginia Commonwealth University (VCU)

Richmond, Virginia, United States, 23298

Actively Recruiting

9

St. Vincent's Hospital

Fitzroy, Victoria, Australia, 3065

Actively Recruiting

10

CHU de Nantes

Nantes, France, 44093

Actively Recruiting

11

Institut de Myologie

Paris, France, 75013

Actively Recruiting

12

Charité - Universitätsmedizin Berlin

Berlin, Germany, 10117

Actively Recruiting

13

Ludwig Maximilians University, Munich - Friedrich Baur Institut

Munich, Germany, 80336

Actively Recruiting

14

Centro Clinico Nemo

Milan, Italy, 20162

Actively Recruiting

15

Fondazione Policlinico Universitario A Gemelli-Rome

Rome, Italy, 00168

Actively Recruiting

16

Radboud Medical Center

Nijmegen, Netherlands

Actively Recruiting

17

NZCR Auckland

Auckland, New Zealand, 1023

Actively Recruiting

18

University College London Hospitals

London, United Kingdom, NW1 2BU

Actively Recruiting

19

John Walton Muscular Dystrophy Research Centre

Newcastle upon Tyne, United Kingdom

Actively Recruiting

20

Salford Royal Hospital

Salford, United Kingdom, M6 8HD

Actively Recruiting

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Research Team

D

Dyne Clinical Trials

How is the study designed?

Study Type

INTERVENTIONAL

Masking

QUADRUPLE

Allocation

RANDOMIZED

Model

SEQUENTIAL

Primary Purpose

TREATMENT

Number of Arms

8

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