Actively Recruiting

Phase 2
Age: 1Day - 6Months
All Genders
ID05104983

Stopping TSC Onset and Progression 2B: Sirolimus TSC Epilepsy Prevention Study

Led by Darcy Krueger · Updated on 2026-01-22

64

Participants Needed

11

Research Sites

52 weeks

Total Duration

On this page

AI-Summary

What this Trial Is About

This research aims to evaluate whether early treatment with sirolimus can prevent or delay the start of seizures in infants with Tuberous Sclerosis Complex (TSC), a genetic condition caused by mutations affecting the mTOR signaling pathway. This Phase II randomized, double-blind, placebo-controlled trial investigates the safety and effects of sirolimus in this high-risk infant population. The study is supported by the US FDA's Office of Orphan Products Division. Participants will be randomly assigned to receive either sirolimus oral suspension or a matching placebo. Treatment begins before infants reach seven months of age and continues while researchers monitor for seizure onset. The study compares the timing of seizures and collects data on safety, neurodevelopment, quality of life, and biological markers through EEG and MRI at 12 and 24 months of age. During the trial, infants will undergo regular assessments including neurological exams, EEG and MRI scans, and developmental evaluations to track seizure onset and brain development. Researchers will monitor safety by recording any adverse events and adjust sirolimus dosing as needed. The primary outcomes focus on the time to first seizure and safety at 12 months, with additional follow-ups to 24 months to assess longer-term effects.

CONDITIONS

Brief Title

Stopping TSC Onset and Progression 2B: Sirolimus TSC Epilepsy Prevention Study

Who Can Participate

Age: 1Day - 6Months
All Genders

Eligibility Criteria

Eligible

You may qualify if you...

  • 0 to 6 months old at enrollment, with corrected age at least 39 weeks
  • Confirmed diagnosis of Tuberous Sclerosis Complex (TSC) by clinical or genetic criteria
Not Eligible

You will not qualify if you...

  • History of seizures or abnormal EEG at enrollment
  • Prior or current treatment with anticonvulsant medications, systemic mTOR inhibitors, ketogenic diets, or other anti-seizure therapies
  • Use of investigational drugs within 30 days before screening
  • Significant illness or active infection at screening
  • History of significant prematurity (gestational age less than 30 weeks) or major medical complications at birth aside from TSC
  • Abnormal baseline lab values deemed unsafe by the investigator
  • Neurosurgery planned or done within 3 months of baseline
  • Presence of TSC-related conditions requiring mTOR treatment (such as SEGA or AML)
  • Inability to comply with study requirements as judged by the investigator

AI-Screening

AI-Powered Screening

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Your Study Journey

Screening

Duration - 2 to 4 weeks

Participants are screened for eligibility to participate in the trial.

1 visit (in-person)

Treatment

Duration - Up to 12 months of age

Participants receive either sirolimus or placebo to evaluate prevention or delay of seizure onset in TSC.

Regular visits during treatment as scheduled by the study team

Follow-up

Duration - Up to 24 months of age

Participants are monitored for neurodevelopmental outcomes, quality of life, and biomarker assessments after treatment ends.

Visits at 12 and 24 months of age

Trial Site Locations

Total: 11 locations

1

University of Alabama at Birmingham

Birmingham, Alabama, United States, 35294

Actively Recruiting

2

University of California at Los Angeles

Los Angeles, California, United States, 90095

Actively Recruiting

3

Stanford University

Palo Alto, California, United States, 94304

Actively Recruiting

4

Children's Hospital Colorado

Aurora, Colorado, United States, 80045

Actively Recruiting

5

Lurie Children's Hospital of Chicago

Chicago, Illinois, United States, 60611

Actively Recruiting

6

Boston Children's Hospital

Boston, Massachusetts, United States, 02115

Actively Recruiting

7

Washington University -- St. Louis

St Louis, Missouri, United States, 63110

Actively Recruiting

8

University of North Carolina at Chapel Hill

Chapel Hill, North Carolina, United States, 27510

Active, Not Recruiting

9

Cincinnati Children's Hospital Medical Center

Cincinnati, Ohio, United States, 45229

Actively Recruiting

10

University of Texas HSC at Houston

Houston, Texas, United States, 77030

Actively Recruiting

11

Seattle Children's Hospital

Seattle, Washington, United States, 98105

Actively Recruiting

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Research Team

M

Molly S Griffith, BA

J

Jessica Krefting, RN

How is the study designed?

Study Type

INTERVENTIONAL

Masking

TRIPLE

Allocation

RANDOMIZED

Model

PARALLEL

Primary Purpose

PREVENTION

Number of Arms

2

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