Actively Recruiting

Phase 1
Phase 2
Age: 0 - 17Years
All Genders
NCT05788536

A Study of DB-OTO, an Adeno-Associated Virus (AAV) Based Gene Therapy, in Children/Infants With Hearing Loss Due to Otoferlin Mutations

Led by Regeneron Pharmaceuticals · Updated on 2026-05-05

30

Participants Needed

16

Research Sites

452 weeks

Total Duration

On this page

AI-Summary

What this Trial Is About

Regeneron is conducting a study of an investigational new drug called DB-OTO. DB-OTO is a gene therapy that is being developed to treat children who have hearing loss due to changes in the otoferlin gene. The purpose of this study is to: * Learn about the safety of DB-OTO * Determine how well DB-OTO is tolerated (does not cause ongoing discomfort) * Evaluate the efficacy of DB-OTO (how well DB-OTO works)

CONDITIONS

Official Title

A Study of DB-OTO, an Adeno-Associated Virus (AAV) Based Gene Therapy, in Children/Infants With Hearing Loss Due to Otoferlin Mutations

Who Can Participate

Age: 0 - 17Years
All Genders

Eligibility Criteria

Eligible

You may qualify if you...

  • At least one parent or legal guardian is willing to provide written informed consent and the patient to provide assent when applicable
  • Willingness to comply with the study protocol, including genetic testing and vaccinations as required
  • Patient is under 18 years old and able to complete necessary assessments for enrollment and dosing
  • Presence of biallelic, likely pathogenic or pathogenic otoferlin (OTOF) gene variants
  • No clinically significant abnormal laboratory test results at screening
  • Profound sensorineural hearing loss (>90 dB HL) diagnosed by behavioral and physiological tests
  • Outer hair cell presence confirmed by otoacoustic emissions or cochlear microphonic depending on age
  • No evidence that hearing loss depends on body temperature
  • Female patients of childbearing potential and fertile males must agree to use effective contraception during short-term follow-up and for specified periods after treatment
Not Eligible

You will not qualify if you...

  • Prior treatment with gene therapy
  • Surgical anatomy that prevents or affects the planned ear injection
  • Other permanent or untreatable hearing loss conditions
  • History or presence of malignancies
  • History or presence of meningitis
  • History or presence of cochlear implants in the ear(s) to be treated
  • History of risk factors for auditory neuropathy not caused by otoferlin mutations, including prematurity, low birth weight, hyperbilirubinemia, NICU admission, or low Apgar scores
  • Other protocol-defined exclusion criteria

AI-Screening

AI-Powered Screening

Complete this quick 3-step screening to check your eligibility

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Trial Site Locations

Total: 16 locations

1

University of California Los Angeles Medical Center

Los Angeles, California, United States, 90024

Actively Recruiting

2

Rady Children's Hospital

San Diego, California, United States, 92123

Actively Recruiting

3

Nemours Children s Clinic

Jacksonville, Florida, United States, 32207

Actively Recruiting

4

Nemours Childrens Hospital

Orlando, Florida, United States, 32827

Actively Recruiting

5

Boston Children's Hospital - Main

Boston, Massachusetts, United States, 02115

Actively Recruiting

6

Columbia University Irving Medical Center

New York, New York, United States, 10032

Actively Recruiting

7

Cincinnati Children's Hospital Medical Center

Cincinnati, Ohio, United States, 45229

Actively Recruiting

8

Seattle Children's Hospital

Seattle, Washington, United States, 98105

Actively Recruiting

9

Medical College of Wisconsin

Milwaukee, Wisconsin, United States, 53226

Actively Recruiting

10

University Hospital Tubingen

Tübingen, Germany, 72076

Actively Recruiting

11

Shinshu University Hospital

Matsumoto-shi, Nagano, Japan, 390-8621

Actively Recruiting

12

Clinica Universidad de Navarra- Pamplona

Pamplona, Navarre, Spain, 31008

Actively Recruiting

13

Hospital Universitario Materno Infantil en las Palmas de Gran Canaria

Las Palmas de Gran Canaria, Spain, 35016

Withdrawn

14

Ramon y Cajal University Hospital

Madrid, Spain, 28034

Actively Recruiting

15

Addenbrooke's Hospital, Cambridge University Hospitals NHS FT

Cambridge, United Kingdom, CB2 0QQ

Actively Recruiting

16

Great Ormond Street Hospital For Children NHS Foundation Trust

London, United Kingdom, WC1N 3JH

Actively Recruiting

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Research Team

C

Clinical Trials Administrator

CONTACT

How is the study designed?

Study Type

INTERVENTIONAL

Masking

NONE

Allocation

NON_RANDOMIZED

Model

SEQUENTIAL

Primary Purpose

TREATMENT

Number of Arms

2

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