Actively Recruiting

Phase 2
Age: 1Year - 39Years
All Genders
ID05465174

Tovorafenib for the Treatment of Newly Diagnosed or Recurrent Craniopharyngioma in Children and Young Adults

Led by Sabine Mueller, MD, PhD · Updated on 2026-04-23

57

Participants Needed

20

Research Sites

52 weeks

Total Duration

On this page

Sponsors

S

Sabine Mueller, MD, PhD

Lead Sponsor

D

Day One Biopharmaceuticals, Inc.

Collaborating Sponsor

AI-Summary

What this Trial Is About

Researchers are evaluating the tolerability and effectiveness of tovorafenib, a pan-RAF-kinase inhibitor, as a single treatment for children and young adults with newly diagnosed or recurrent craniopharyngioma. This phase 2 study aims to determine progression-free survival and maintenance of quality of life over 12 months, comparing results with historical data. The study also explores visual and neuroendocrine function over several years and investigates changes in tumor biology and patient satisfaction during therapy. Participants are divided into two groups: those with newly diagnosed craniopharyngioma and those with recurrent disease. All participants undergo biopsy or resection as standard care. Before surgery, patients receive one dose of tovorafenib. Those with measurable disease after surgery continue weekly maintenance doses. Those with complete tumor removal enter a follow-up phase. Non-surgical recurrent cases also receive weekly tovorafenib. Treatment is oral and given at a recommended phase 2 dose. Throughout the study, participants complete physical function and quality of life assessments, as well as visual and neuroendocrine evaluations at set intervals up to five years. Tissue and fluid samples collected before and after treatment help researchers study tumor changes at molecular levels. Patient-reported outcomes assess satisfaction and therapy-related side effects in context of social and racial factors. Safety is monitored continuously, and participation may last several years depending on follow-up needs.

CONDITIONS

Brief Title

Tovorafenib for Treatment of Craniopharyngioma in Children and Young Adults

Who Can Participate

Age: 1Year - 39Years
All Genders

Eligibility Criteria

Eligible

You may qualify if you...

  • Newly diagnosed craniopharyngioma based on imaging and central review
  • Recurrent craniopharyngioma with histologic confirmation or imaging consistent with diagnosis
  • Age between 1 and 39 years
  • Surgical candidates planned for biopsy or resection or with available archival tumor tissue
  • Measurable disease for participants continuing maintenance therapy
  • Karnofsky score ≥ 50 (age > 16) or Lansky score ≥ 50 (age ≤ 16)
  • Stable or decreasing corticosteroid use, with dose limits
  • Adequate bone marrow, renal, liver, neurologic, and pulmonary function
  • Willingness to use effective contraception if applicable
  • Ability to understand and sign informed consent and complete quality of life assessments
Not Eligible

You will not qualify if you...

  • Previous tumor-directed therapy for newly diagnosed participants
  • Chemotherapy or radiotherapy within 3 weeks prior to study entry (6 weeks for some drugs)
  • Recent use of biologic or monoclonal antibody treatments within specified washout periods
  • Rapidly progressive symptoms requiring urgent surgery or radiation
  • Uncontrolled neuroendocrine dysfunction
  • Significant active cardiovascular disease or recent heart events
  • Allergic reactions to similar compounds as tovorafenib
  • Severe nausea, vomiting, or malabsorption preventing adequate absorption
  • Uncontrolled infections or other illnesses
  • Current use of other investigational agents
  • Pregnancy or breastfeeding in women of childbearing potential
  • Use of strong CYP2C8 inhibitors or inducers not allowed by study
  • Inability to return for follow-up visits or assessments required by the study

AI-Screening

AI-Powered Screening

Complete this quick 3-step screening to check your eligibility

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Your Study Journey

Screening

Duration - 2 to 4 weeks

Participants are screened for eligibility to participate in the trial.

1 visit (in-person)

Run-in Period

Duration - 7 days ± 2 days

Participants receive one dose of tovorafenib within 7 days prior to their planned biopsy or resection.

1 visit (in-person) for dosing prior to biopsy or resection

Treatment

Duration - Ongoing weekly dosing until disease progression or discontinuation

Participants undergo biopsy or resection and those with measurable disease continue on maintenance tovorafenib once weekly. Participants with gross total resection enter follow-up only.

Weekly visits for treatment and monitoring

Follow-up

Duration - Up to 5 years

Participants with gross total resection or those completing treatment are monitored for progression free survival, quality of life, and long-term visual and neuroendocrine function.

Periodic visits for up to 5 years for assessments

Trial Site Locations

Total: 20 locations

1

University of Alabama at Birmingham

Birmingham, Alabama, United States, 35294

Actively Recruiting

2

Rady Children's Hospital/University of California, San Diego

San Diego, California, United States, 92037

Actively Recruiting

3

University of California, San Francisco

San Francisco, California, United States, 94143

Actively Recruiting

4

University of Florida

Gainesville, Florida, United States, 32611

Actively Recruiting

5

Ann & Robert H. Lurie Children's Hospital of Chicago

Chicago, Illinois, United States, 60611

Actively Recruiting

6

Riley Hospital for Children at Indiana University Health

Indianapolis, Indiana, United States, 46202

Actively Recruiting

7

John Hopkins University

Baltimore, Maryland, United States, 21218

Actively Recruiting

8

Dana-Farber/Boston Children's Harvard Medical School

Boston, Massachusetts, United States, 02215

Actively Recruiting

9

University of Michigan

Ann Arbor, Michigan, United States, 48109

Actively Recruiting

10

Children's Minnesota

Minneapolis, Minnesota, United States, 55404

Actively Recruiting

11

St. Louis Children's Hospital Washington University

St Louis, Missouri, United States, 63110

Actively Recruiting

12

NYU Langone Health

New York, New York, United States, 10016

Actively Recruiting

13

Duke University Medical Center

Durham, North Carolina, United States, 27710

Actively Recruiting

14

Children's Hospital of Philadelphia

Philadelphia, Pennsylvania, United States, 19103

Actively Recruiting

15

University of Utah

Salt Lake City, Utah, United States, 84112

Actively Recruiting

16

John Hunter Children's Hospital

New Lambton Heights, New South Wales, Australia, 2310

Actively Recruiting

17

Royal Hobart Hospital

Hobart, Tasmania, Australia, 7000

Actively Recruiting

18

Children's Cancer Centre, Monash Children's Hospital

Clayton, VIC 3168, Australia

Actively Recruiting

19

Royal Children's Hospital, Childrens' Cancer Centre

Parkville, Victoria, Australia, 3052

Actively Recruiting

20

Perth Children's Hospital

Nedlands, Western Australia, Australia, 6009

Actively Recruiting

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Research Team

P

PNOC Operations Office

How is the study designed?

Study Type

INTERVENTIONAL

Masking

NONE

Allocation

NON_RANDOMIZED

Model

PARALLEL

Primary Purpose

TREATMENT

Number of Arms

3

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